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Comparative case report of segmental odontomaxillary dysplasia and regional odontodysplasia Stephanie L Clark Alison M Cairns Keith D Hunter Dental Update 2024 41:9, 707-709.
Authors
Stephanie LClark
BDS, MFDS RCPSG, MPaedDent
Specialist Paediatric Dentist, Glasgow Dental Hospital and School
The clinical and radiological features of segmental odontomaxillary dysplasia (SOD) are well described but the condition is probably under recognized owing to misdiagnosis as an atypical form of regional odontodysplasia (ROD). Two cases are compared to highlight the differences between SOD and ROD. The clinical, radiographic and histological findings are compared using case reports of a 6-year-old male with SOD and a 4-year-old girl with ROD. Treatment and follow-up for these patients is described, along with a comparative review of the major characteristics of these two rare conditions.
Clinical Relevance: To help the paediatric dentist distinguish between these two rare conditions.
Article
Developmental disorders involving segments of the developing dentition and their associated structures are rare and, consequently, there is potential for confusion to arise. Two such conditions are segmental odontomaxillary dysplasia (SOD) and regional odontodysplasia (ROD).
SOD is a rare unilateral developmental disorder of the maxilla, involving abnormal growth and maturation of the bone, the teeth and covering gingiva. There are specific clinical, radiographic and histological characteristics. The condition was initially reported as hemimaxillofacial dysplasia by Miles et al in 1987.1 This was revised by Danforth et al in 19902 to the current definition which takes better account of the dental findings.
A review of the literature by Prusack et al3 in 2000 reported 26 cases of SOD. They found SOD to be a non-progressive developmental disorder limited to a posterior segment of the maxilla, resulting in:
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